Abstract

The neuropathological hallmarks of Parkinson’s disease include preferential vulnerability of dopaminergic neurons of the substantia nigra pars compacta, and accumulation of intraneuronal protein inclusions known as Lewy bodies. These inclusions contain, among other proteins, aggregated alpha-synuclein and histone deacetylase 6 (HDAC6). In our study we found that selective inhibition of HDAC6 activity by Tubastatin A has protective effects in a rat model of Parkinson’s disease. We provide evidence that this protection may be due to the activation of chaperone-mediated autophagy through the up-regulation of key members of this pathway. Moreover, Tubastatin A significantly inhibited the expression of a toxic form of alpha-synuclein that is phosphorylated at serine position 129. Tubastatin A treatment also permitted to partially modulate neuroinflammation. Taken together, our study highlights the neuroprotective effects of Tubastatin A in a rat model of Parkinson’s disease and provides mechanistic insight in Tubastatin A-mediated protection against alpha-synuclein toxicity and substantia nigra degeneration. These findings are of potential therapeutic value in Parkinson’s disease and other synucleinopathies.

Details

Title
Inhibition of HDAC6 activity protects dopaminergic neurons from alpha-synuclein toxicity
Author
Francelle Laetitia 1 ; Outeiro, Tiago F 2 ; Rappold, Gudrun A 3 

 Ruprecht-Karls-University Heidelberg, Department of Human Molecular Genetics, Institute of Human Genetics, Heidelberg, Germany (GRID:grid.7700.0) (ISNI:0000 0001 2190 4373); University Medical Center Goettingen, Department of Experimental Neurodegeneration, Center for Biostructural Imaging of Neurodegeneration, Goettingen, Germany (GRID:grid.411984.1) (ISNI:0000 0001 0482 5331) 
 University Medical Center Goettingen, Department of Experimental Neurodegeneration, Center for Biostructural Imaging of Neurodegeneration, Goettingen, Germany (GRID:grid.411984.1) (ISNI:0000 0001 0482 5331); Max Planck Institute for Experimental Medicine, Goettingen, Germany (GRID:grid.419522.9) (ISNI:0000 0001 0668 6902) 
 Ruprecht-Karls-University Heidelberg, Department of Human Molecular Genetics, Institute of Human Genetics, Heidelberg, Germany (GRID:grid.7700.0) (ISNI:0000 0001 2190 4373) 
Publication year
2020
Publication date
2020
Publisher
Nature Publishing Group
e-ISSN
20452322
Source type
Scholarly Journal
Language of publication
English
ProQuest document ID
2387630606
Copyright
© The Author(s) 2020. This work is published under http://creativecommons.org/licenses/by/4.0/ (the “License”). Notwithstanding the ProQuest Terms and Conditions, you may use this content in accordance with the terms of the License.