Abstract

Background

Niemann-Pick disease (NPD) is a rare autosomal recessive hereditary disease characterized by deficient activity of acid sphingomyelinase.

Case presentation

We present a case of NPD type B with a unique compound heterozygosity for SMPD1 (NM_000543.4:c.[84delC];[96G > A]) in which both mutations that induce an early stop codon are located before the second in-frame initiation codon. The clinical presentation of the patient is compatible with NPD type B. She was initially diagnosed of Gaucher Disease, but her altered lipid profile led to a clinical suspicion of NPD.

Combined high doses of atorvastatin and ezetimibe were given to treat the severe hypercholesterolemia.

Conclusions

The pharmacological management of the lipid profile in these patients is important. A unique compound mutation in SMPD1 gene is described.

Details

Title
Niemann-Pick disease type-B: a unique case report with compound heterozygosity and complicated lipid management
Author
Ordieres-Ortega, L; Galeano-Valle, F; Mallén-Pérez, M; Muñoz-Delgado, C; Apaza-Chavez, J E; Menárguez-Palanca, F J; Alvarez-Sala Walther, L A; Demelo-Rodríguez, P
Pages
1-6
Section
Case report
Publication year
2020
Publication date
2020
Publisher
BioMed Central
e-ISSN
14712350
Source type
Scholarly Journal
Language of publication
English
ProQuest document ID
2404396200
Copyright
© 2020. This work is licensed under http://creativecommons.org/licenses/by/4.0/ (the “License”). Notwithstanding the ProQuest Terms and Conditions, you may use this content in accordance with the terms of the License.